A new variant of the ectodysplasin A receptor death domain gene associated with anhidrotic ectodermal dysplasia in a Turkish family and its simple diagnosis by restriction fragment length polymorphism

Ectodermal dysplasia (ED), which exhibits a wide range of clinical symptoms, may be classified into three major types: hypohidrotic, anhidrotic, and hidrotic. A male child (proband) showing anhidrotic dysplasia was used as the subject of this study. The biopsy of the big toe revealed that the male c...

Ausführliche Beschreibung

Gespeichert in:
Bibliographische Detailangaben
Veröffentlicht in:Genes & Genetic Systems Jg. 98; H. 4; S. 171 - 178
Hauptverfasser: Rencuzogullari, Eyyup, Ezer, Banu Guven
Format: Journal Article
Sprache:Englisch
Veröffentlicht: Japan The Genetics Society of Japan 01.08.2023
Japan Science and Technology Agency
Schlagworte:
ISSN:1341-7568, 1880-5779, 1880-5779
Online-Zugang:Volltext
Tags: Tag hinzufügen
Keine Tags, Fügen Sie den ersten Tag hinzu!
Abstract Ectodermal dysplasia (ED), which exhibits a wide range of clinical symptoms, may be classified into three major types: hypohidrotic, anhidrotic, and hidrotic. A male child (proband) showing anhidrotic dysplasia was used as the subject of this study. The biopsy of the big toe revealed that the male child had no sweat glands. Genetic analysis of the patient revealed a mutation caused by a homozygous nucleotide substitution in the EDAR-associated death domain (EDARADD) (rs114632254) gene c.439G>A (p.Gly147Arg). Phenotypically, his teeth were sharp, but eight teeth were missing (oligodontia). The patient had normal nails with dry skin, sparse hair, everted lower lip vermilion, hyperpigmented eyelids, and abnormal nasal bridge morphology around the eyes. There is also a homozygous dominant (healthy) female and a heterozygous male in this family, who are cousins (aunt children) to the heterozygous parents. The daughter of the patient was also heterozygous. This mutation represents homozygous recessive inheritance, which we describe for the first time. Furthermore, we demonstrated that this genetic disorder can be readily diagnosed using the restriction fragment length polymorphism (RFLP) method after digestion with MnII restriction endonuclease.
AbstractList Ectodermal dysplasia (ED), which exhibits a wide range of clinical symptoms, may be classified into three major types: hypohidrotic, anhidrotic, and hidrotic. A male child (proband) showing anhidrotic dysplasia was used as the subject of this study. The biopsy of the big toe revealed that the male child had no sweat glands. Genetic analysis of the patient revealed a mutation caused by a homozygous nucleotide substitution in the EDAR-associated death domain (EDARADD) (rs114632254) gene c.439G>A (p.Gly147Arg). Phenotypically, his teeth were sharp, but eight teeth were missing (oligodontia). The patient had normal nails with dry skin, sparse hair, everted lower lip vermilion, hyperpigmented eyelids, and abnormal nasal bridge morphology around the eyes. There is also a homozygous dominant (healthy) female and a heterozygous male in this family, who are cousins (aunt children) to the heterozygous parents. The daughter of the patient was also heterozygous. This mutation represents homozygous recessive inheritance, which we describe for the first time. Furthermore, we demonstrated that this genetic disorder can be readily diagnosed using the restriction fragment length polymorphism (RFLP) method after digestion with MnII restriction endonuclease.
Ectodermal dysplasia (ED), which exhibits a wide range of clinical symptoms, may be classified into three major types: hypohidrotic, anhidrotic, and hidrotic. A male child (proband) showing anhidrotic dysplasia was used as the subject of this study. The biopsy of the big toe revealed that the male child had no sweat glands. Genetic analysis of the patient revealed a mutation caused by a homozygous nucleotide substitution in the EDAR-associated death domain (EDARADD) (rs114632254) gene c.439G>A (p.Gly147Arg). Phenotypically, his teeth were sharp, but eight teeth were missing (oligodontia). The patient had normal nails with dry skin, sparse hair, everted lower lip vermilion, hyperpigmented eyelids, and abnormal nasal bridge morphology around the eyes. There is also a homozygous dominant (healthy) female and a heterozygous male in this family, who are cousins (aunt children) to the heterozygous parents. The daughter of the patient was also heterozygous. This mutation represents homozygous recessive inheritance, which we describe for the first time. Furthermore, we demonstrated that this genetic disorder can be readily diagnosed using the restriction fragment length polymorphism (RFLP) method after digestion with MnII restriction endonuclease.Ectodermal dysplasia (ED), which exhibits a wide range of clinical symptoms, may be classified into three major types: hypohidrotic, anhidrotic, and hidrotic. A male child (proband) showing anhidrotic dysplasia was used as the subject of this study. The biopsy of the big toe revealed that the male child had no sweat glands. Genetic analysis of the patient revealed a mutation caused by a homozygous nucleotide substitution in the EDAR-associated death domain (EDARADD) (rs114632254) gene c.439G>A (p.Gly147Arg). Phenotypically, his teeth were sharp, but eight teeth were missing (oligodontia). The patient had normal nails with dry skin, sparse hair, everted lower lip vermilion, hyperpigmented eyelids, and abnormal nasal bridge morphology around the eyes. There is also a homozygous dominant (healthy) female and a heterozygous male in this family, who are cousins (aunt children) to the heterozygous parents. The daughter of the patient was also heterozygous. This mutation represents homozygous recessive inheritance, which we describe for the first time. Furthermore, we demonstrated that this genetic disorder can be readily diagnosed using the restriction fragment length polymorphism (RFLP) method after digestion with MnII restriction endonuclease.
ArticleNumber 22-00138
Author Rencuzogullari, Eyyup
Ezer, Banu Guven
Author_xml – sequence: 1
  fullname: Rencuzogullari, Eyyup
  organization: Department of Biology, Science and Letters Faculty, Adiyaman University
– sequence: 1
  fullname: Ezer, Banu Guven
  organization: Department of Biology, Institute of Graduate Education, Adiyaman University
BackLink https://www.ncbi.nlm.nih.gov/pubmed/37673591$$D View this record in MEDLINE/PubMed
BookMark eNpdkk1v1DAQhiNURD_gxhlZ4sKBFH8kTnwsFV9SJS7lbE2cSeIlsYPtbbX_kJ-Ft9vdAxd7NPO8MyPNe1mcOe-wKN4yes24lJ_GMV5zXlLKRPuiuGBtS8u6adRZjkXFyqaW7XlxGeOGUk5VK14V56KRjagVuyj-3hCHj-QBggWXiB9ImpCgSb7fxXWGaB25IQENrskH0iOkifR-gZwf0SGBGL2xkLAnjzbXwE22Dz5Zc-iCYYGZHJsByTog99vw28aJDLDYeZc1PbEpkmiXdUbSWxidjzaSbpdHxxSsSdY7MgQYF8xrzujGPGv1827xYZ1sXF4XLweYI755_q-KX1-_3N9-L-9-fvtxe3NXmkqKVMpBMjnQXslaMma4MFU1MIY8RzXWDRWdYIAVZzV0Erva9ExxCZXqFGcVE1fFh0PfNfg_27ycXmw0OM_g0G-j5q3kTKmGiYy-_w_d-G1weTvNFWWqaXizp949U9tuwV6vwS4Qdvp4owx8PAAm-BgDDieEUb23gM4W0JzrJwtk_PMB38QEI55gCPkmMz7BqtXV_jmKTkUzQdDoxD8tBL79
Cites_doi 10.1111/j.1365-263X.2006.00801.x
10.1038/414913a
10.1002/ajmg.1320310106
10.1002/ajmg.a.10929
10.1093/nar/gky1016
10.1016/j.jmoldx.2011.07.008
10.1111/j.1525-1470.1988.tb01162.x
10.1038/gim.2015.30
10.1086/301984
10.1016/S1607-551X(09)70303-1
10.1002/ajmg.a.37607
10.1136/jmg.18.6.459
10.3390/genes12091389
10.1177/0022034513487210
10.1002/ajmg.a.37412
10.1002/humu.20500
10.1016/S1472-6483(11)60543-9
10.1038/s41586-020-2308-7
10.1038/11937
10.1016/j.ijporl.2013.06.027
10.1093/nar/gkx1153
10.1038/jhg.2016.75
10.1159/000346610
10.1111/ced.12248
10.1177/0022034513487557
10.1002/ajmg.a.32855
10.1136/jmg.12.3.308
10.3892/ijmm.2016.2742
10.1016/S0960-9822(02)00687-5
10.1002/humu.21384
10.1159/000251442
10.1111/j.1365-2133.2010.09670.x
10.14715/cmb/2017.63.8.12
10.1007/s10875-013-9924-z
10.1182/blood-2011-05-354167
10.1093/hmg/ddi405
10.1111/j.1601-6343.2010.01484.x
10.1016/j.gene.2011.10.009
10.1111/j.1440-0960.2010.00685.x
10.1002/humu.22271
10.1016/j.jaad.2005.10.002
10.1016/S1695-4033(02)77793-X
10.1111/1346-8138.12077
10.1016/j.smim.2014.05.002
10.1016/j.ijporl.2013.09.004
10.1111/jdv.12493
10.1186/s13023-019-1251-x
10.1182/blood-2003-10-3655
10.1111/bjd.12151
10.1002/ajmg.a.33164
ContentType Journal Article
Copyright 2023 The Author(s).
2023. This work is published under https://creativecommons.org/licenses/by/4.0/legalcode (the “License”). Notwithstanding the ProQuest Terms and Conditions, you may use this content in accordance with the terms of the License.
Copyright_xml – notice: 2023 The Author(s).
– notice: 2023. This work is published under https://creativecommons.org/licenses/by/4.0/legalcode (the “License”). Notwithstanding the ProQuest Terms and Conditions, you may use this content in accordance with the terms of the License.
DBID AAYXX
CITATION
CGR
CUY
CVF
ECM
EIF
NPM
7SS
7TK
8FD
FR3
K9.
NAPCQ
P64
RC3
7X8
DOI 10.1266/ggs.22-00138
DatabaseName CrossRef
Medline
MEDLINE
MEDLINE (Ovid)
MEDLINE
MEDLINE
PubMed
Entomology Abstracts (Full archive)
Neurosciences Abstracts
Technology Research Database
Engineering Research Database
ProQuest Health & Medical Complete (Alumni)
Nursing & Allied Health Premium
Biotechnology and BioEngineering Abstracts
Genetics Abstracts
MEDLINE - Academic
DatabaseTitle CrossRef
MEDLINE
Medline Complete
MEDLINE with Full Text
PubMed
MEDLINE (Ovid)
Entomology Abstracts
Nursing & Allied Health Premium
Genetics Abstracts
Technology Research Database
ProQuest Health & Medical Complete (Alumni)
Engineering Research Database
Neurosciences Abstracts
Biotechnology and BioEngineering Abstracts
MEDLINE - Academic
DatabaseTitleList MEDLINE
MEDLINE - Academic

Entomology Abstracts
Database_xml – sequence: 1
  dbid: NPM
  name: PubMed
  url: http://www.ncbi.nlm.nih.gov/entrez/query.fcgi?db=PubMed
  sourceTypes: Index Database
– sequence: 2
  dbid: 7X8
  name: MEDLINE - Academic
  url: https://search.proquest.com/medline
  sourceTypes: Aggregation Database
DeliveryMethod fulltext_linktorsrc
Discipline Biology
EISSN 1880-5779
EndPage 178
ExternalDocumentID 37673591
10_1266_ggs_22_00138
article_ggs_98_4_98_22_00138_article_char_en
Genre Journal Article
GroupedDBID ---
-~X
.55
29H
2WC
36B
53G
5GY
ACGFO
ACPRK
ADBBV
AENEX
AHMBA
ALMA_UNASSIGNED_HOLDINGS
BAWUL
BKOMP
CS3
DIK
DU5
E3Z
EBD
EBS
EJD
EMB
EMOBN
F5P
GROUPED_DOAJ
GX1
JMI
JSF
JSH
KQ8
L7B
MOJWN
OK1
OVT
PQQKQ
RJT
RNS
RZJ
SV3
TR2
W2D
X7M
XSB
AAYXX
CITATION
CGR
CUY
CVF
ECM
EIF
NPM
7SS
7TK
8FD
FR3
K9.
NAPCQ
P64
RC3
7X8
ID FETCH-LOGICAL-c463t-6f616f0d965611c23c44f11e223c5e5703b31ae4215ab6eb5cd1926a49b921413
ISICitedReferencesCount 1
ISICitedReferencesURI http://www.webofscience.com/api/gateway?GWVersion=2&SrcApp=Summon&SrcAuth=ProQuest&DestLinkType=CitingArticles&DestApp=WOS_CPL&KeyUT=001072006300001&url=https%3A%2F%2Fcvtisr.summon.serialssolutions.com%2F%23%21%2Fsearch%3Fho%3Df%26include.ft.matches%3Dt%26l%3Dnull%26q%3D
ISSN 1341-7568
1880-5779
IngestDate Thu Oct 02 11:30:55 EDT 2025
Tue Oct 07 06:27:16 EDT 2025
Mon Jul 21 05:52:20 EDT 2025
Sat Nov 29 06:43:46 EST 2025
Wed Sep 03 06:30:47 EDT 2025
IsDoiOpenAccess true
IsOpenAccess true
IsPeerReviewed true
IsScholarly true
Issue 4
Keywords EDARADD
new mutation
anhidrotic
MnII restriction endonuclease
ectodermal dysplasia
Language English
License https://creativecommons.org/licenses/by/4.0/legalcode
LinkModel OpenURL
MergedId FETCHMERGED-LOGICAL-c463t-6f616f0d965611c23c44f11e223c5e5703b31ae4215ab6eb5cd1926a49b921413
Notes ObjectType-Article-1
SourceType-Scholarly Journals-1
ObjectType-Feature-2
content type line 14
content type line 23
OpenAccessLink http://dx.doi.org/10.1266/ggs.22-00138
PMID 37673591
PQID 2901977273
PQPubID 1996350
PageCount 8
ParticipantIDs proquest_miscellaneous_2862199713
proquest_journals_2901977273
pubmed_primary_37673591
crossref_primary_10_1266_ggs_22_00138
jstage_primary_article_ggs_98_4_98_22_00138_article_char_en
PublicationCentury 2000
PublicationDate 2023/08/01
PublicationDateYYYYMMDD 2023-08-01
PublicationDate_xml – month: 08
  year: 2023
  text: 2023/08/01
  day: 01
PublicationDecade 2020
PublicationPlace Japan
PublicationPlace_xml – name: Japan
– name: Mishima
PublicationTitle Genes & Genetic Systems
PublicationTitleAlternate Genes Genet. Syst.
PublicationYear 2023
Publisher The Genetics Society of Japan
Japan Science and Technology Agency
Publisher_xml – name: The Genetics Society of Japan
– name: Japan Science and Technology Agency
References Mikkola, M. L. (2009) Molecular aspects of hypohidrotic ectodermal dysplasia. Am. J. Med. Genet. A 149A, 2031–2036.
Norval, E. J., van Wyk, C. W., Basson, N. J., and Coldrey, J. (1988) Hypohidrotic ectodermal dysplasia: a genealogic, stereomicroscope, and scanning electron microscope study. Pediatr. Dermatol. 5, 159–166.
Feng, H.-l., Zhang, X.-x., and Wu, H. (2007) Research advances in tooth agenesis. Journal of Peking University, Health sciences 39, 13–17 (in Chinese).
Ersoy-Evans, S., Erkin, G., Fassihi, H., Chan, I., Paller, A. S., Sürücü, S., and McGrath, J. A. (2006) Ectodermal dysplasia-skin fragility syndrome resulting from a new homozygous mutation, 888delC, in the desmosomal protein plakophilin 1. J. Am. Acad. Dermatol. 55, 157–161.
Sun, X., Shen, J., Wu, W., Xie, J., Gao, C., Qin, L., Cui, Y., and Liu, J. (2013) Identification of a novel c.822 G>T mutation of EDA gene in a Chinese family with X-linked hypohidrotic ectodermal dysplasia. Chinese journal of medical genetics 30, 270–273 (in Chinese).
Cluzeau, C., Hadj-Rabia, S., Jambou, M., Mansour, S., Guigue, P., Masmoudi, S., Bal, E., Chassaing, N., Vincent, M.-C., Viot, G., et al. (2011) Only four genes (EDA1, EDAR, EDARADD, and WNT10A) account for 90% of hypohidrotic/anhidrotic ectodermal dysplasia cases. Hum. Mutat. 32, 70–72.
Barbaro, V., Confalonieri, L., Vallini, I., Ferrari, S., Ponzin, D., Mantero, G., Willoughby, C. E., Parekh, M., and Di Iorio, E. (2012) Development of an allele-specific real-time PCR assay for discrimination and quantification of p63 R279H mutation in EEC syndrome. J. Mol. Diagn. 14, 38–45.
Bibi, N., Ahmad, S., Ahmad, W., and Naeem, M. (2011) Molecular genetic analysis of consanguineous Pakistani families with autosomal recessive hypohidrotic ectodermal dysplasia. Australas J. Dermatol. 52, 37–42.
Wohlfart, S., Söder, S, Smahi, A., and Schneider, H. (2016a) A novel missense mutation in the gene EDARADD associated with an unusual phenotype of hypohidrotic ectodermal dysplasia. Am. J. Med. Genet. A 170A, 249–253.
Li, W., Gao, B.-d., Li, L.-y., Xiao, H. M., and Lu, G.-x. (2006) Mutation screening and prenatal diagnosis of hidrotic ectodermal dysplasia in a Chinese family. Chinese journal of medical genetics 23, 618–621 (in Chinese).
Baskan, Z., Yavuz, I., Ulku, R., Kaya, S., Yavuz, Y., Basaran, G., Adiguzel, O., and Ozer, T. (2006) Evaluation of ectodermal dysplasia. Kaohsiung J. Med. Sci. 22, 171–176.
Martínez-Romero, M. C., Ballesta-Martínez, M. J., López-González, V., Sánchez-Soler, M. J., Serrano-Antón, A. T., Barreda-Sánchez, M., Rodriguez-Peña, L., Martínez-Menchon, M. T., Frías-Iniesta, J., Sánchez-Pedreño, P., et al. (2019) EDA, EDAR, EDARADD and WNT10A allelic variants in patients with ectodermal derivative impairment in the Spanish population. Orphanet J. Rare Dis. 14, 281–291.
Lexner, M. O., Bardow, A., Hertz, J. M., Nielsen, L. A., and Kreiborg, S. (2007) Anomalies of tooth formation in hypohidrotic ectodermal dysplasia. Int. J. Paediatr. Dent. 17, 10–18.
Yan, M., Zhang, Z., Brady, J. R., Schilbach, S., Fairbrother, W. J., and Dixit, V. M. (2002) Identification of a novel death domain-containing adaptor molecule for ectodysplasin-A receptor that is mutated in crinkled mice. Curr. Biol. 12, 409–413.
Chassaing, N., Cluzeau, C., Bal, E., Guigue, P., Vincent, M.-C., Viot, G., Ginisty, D., Munnich, A., Smahi, A., and Calvas, P. (2010) Mutations in EDARADD account for a small proportion of hypohidrotic ectodermal dysplasia cases. Br. J. Dermatol. 162, 1044–1048.
Liu, Y., Yu, X., Wang, L., Li, C., Archacki, S., Huang, C., Liu, J. Y., Wang, Q., Liu, M., and Tang, Z. (2012) Mutation p.Leu354Pro in EDA causes severe hypohidrotic ectodermal dysplasia in a Chinese family. Gene 491, 246–250.
Keng, S. B. (1984) Oro-facial manifestation of hypohidrotic ectodermal dysplasia—case report. Ann. Acad. Med. Singap. 13, 552–555.
Chen, L., Zhao, Y.-y., Wei, Y., Wang, Y., Zhang, Y., Wang, Y.-q., Liu, J.-y., Yang, Y., and Tan, Y.-h. (2012) Prenatal diagnosis of anhidrotic ectodermal dysplasia with unconventional loci abnormalities, a case report. Chin. Med. J. 125, 3177–3179.
Liu, N., Shi, H.-r., Wu, Q.-h., Jiang, M., and Kong, X.-d. (2013) Mutation analysis and first-trimester prenatal diagnosis for a Chinese family with hidrotic ectodermal dysplasia. Chinese journal of medical genetics 30, 407–409.
Monreal, A. W., Zonana, J., and Ferguson, B. (1998) Identification of a new splice form of the EDA1 gene permits detection of nearly all X-linked hypohidrotic ectodermal dysplasia mutations. Am. J. Hum. Genet. 63, 380–399.
Rifai, L., Port-Lis, M., Tabet, A. C., Bailleul-Forestier, I., Benzacken, B., Drunat, S., Kuzbari, S., Passemard, S., Verloes, A., and Aboura, A. (2010) Ectodermal dysplasia-like syndrome with mental retardation due to contiguous gene deletion: further clinical and molecular delineation of del(2q32) syndrome. Am. J. Med. Genet. A 152A, 111–117.
Kawai, T., Nishikomori, R., Izawa, K., Murata, Y., Tanaka, N., Sakai, H., Saito, M., Yasumi, T., Takaoka, Y., Nakahata, T., et al. (2012) Frequent somatic mosaicism of NEMO in T cells of patients with X-linked anhidrotic ectodermal dysplasia with immunodeficiency. Blood 119, 5458–5466.
Callea, M., Teggi, R., Yavuz, I., Tadini, G., Priolo, M., Crovella, S., Clarich, G., and Grasso, D. L. (2013) Ear nose throat manifestations in hypoidrotic ectodermal dysplasia. Int. J. Pediatr. Otorhinolaryngol. 77, 1801–1804.
Nishikomori, R., Akutagawa,H., Maruyama, K., Nakata-Hizume, M., Ohmori, K., Mizuno, K., Yachie, A., Yasumi, T., Kusunoki, T., Heike, T., et al. (2004) X-linked ectodermal dysplasia and immunodeficiency caused by reversion mosaicism of NEMO reveals a critical role for NEMO in human T-cell development and/or survival. Blood 103, 4565–4572.
Nikopensius, T., Annilo, T., Jagomägi, T., Gilissen, C., Kals, M., Krjutškov, K., Mägi, R., Eelmets, M., Gerst-Talas, U., Remm, M., et al. (2013) Non-syndromic tooth agenesis associated with a nonsense mutation in ectodysplasin-A (EDA). J. Dent. Res. 92, 507–511.
Aydin, M., Rencuzogullari, E., Bayram, S., Sevgiler, Y., and Genc, A. (2017) Alterations on high HbF levels may be associated with KLF1 gene mutations. Cell. Mol. Biol. 63, 51–57.
Farooq, M., Kurban, M., Fujimoto, A., Fujikawa, H., Abbas, O., Nemer, G., Saliba, J., Sleiman, R., Tofaili, M., Kibbi, A.-G., et al. (2013) A homozygous frameshift mutation in the HOXC13 gene underlies pure hair and nail ectodermal dysplasia in a Syrian family. Hum. Mutat. 34, 578–581.
Mousumi, T., Xiong, Z., Lu, L., Liu, S., Xia, K., and Hu, Z. (2013) Identification of a known GJB6 mutation in an autosomal dominant inherited Chinese family with hidrotic ectodermal dysplasia. Journal of Central South University, Medical sciences 38, 761–765.
Yin, W., Ye, X., and Bian, Z. (2013) The second deletion mutation in exon 8 of EDA gene in an XLHED pedigree. Dermatology 226, 105–110.
Rentzsch, P., Witten, D., Cooper, G. M., Shendure, J., and Kircher, M. (2019) CADD: predicting the deleteriousness of variants throughout the human genome. Nucleic Acids Res. 47, D886–D894.
Rodewald, A., and Zahn-Messow, K. (1982) Dermatoglyphics findings in families with X-linked hypohidrotic (or anhidrotic) ectodermal dysplasia (HED). Prog. Clin. Biol. Res. 84, 451–458.
Schindler, A., Guazzarotti, L., Mameli, C., Urbani, E., Mozzanica, F., Guerrini, L., and Zuccotti, G. V. (2013) Vomer aplasia in a patient carrying a de novo mutation of the TP63 gene (3q27). Int. J. Pediatr. Otorhinolaryngol. 77, 1606–1608.
Chaudhary, A. K., Girisha, K. M., and Bashyam, M. D. (2016) A novel EDARADD 5’-splice site mutation resulting in activation of two alternate cryptic 5’-splice sites causes autosomal recessive Hypohidrotic Ectodermal Dysplasia. Am. J. Med. Genet. A 170, 1639–1641.
Haghighi, A., Nikuei, P., Haghighi-Kakhki, H., Saleh-Gohari, N., Baghestani, S., Krawitz, P. M., Hecht, J., and Mundlos, S. (2013) Whole-exome sequencing identifies a novel missense mutation in EDAR causing autosomal recessive hypohidrotic ectodermal dysplasia with bilateral amastia and palmoplantar hyperkeratosis. Br. J. Dermatol. 168, 1353–1356.
Potter, P. C., and Bowie, M. D. (1984) Dysphagia in hypohidrotic ectodermal dysplasia. A case report. S. Afr. Med. J. 66, 232–234.
Yang, Y., Luo, L., Xu, J., Zhu, P., Xue, W., Wang, J., Li, W., Wang, M., Cheng, K., Liu, S., et al. (2013) Novel EDA p.Ile260Ser mutation linked to non-syndromic hypodontia. J. Dent. Res. 92, 500–506.
Hayashi, R., Farooq, M., Fujikawa, H., Fujimoto, A., Hashimoto, T., Ito, M., and Shimomura, Y. (2013) Case of hypohidrotic ectodermal dysplasia caused by a large deletion mutation in the EDA gene. J. Dermatol. 40, 281–283.
Shi, H.-j., Fang, Q., and Wang, L.-t. (2005) Prenatal diagnosis of X-linked anhidrotic ectodermal dysplasia with X-chromosome inversion. Chin Med. J. 85, 1845–1848 (in Chinese).
Richards, S., Aziz, N., Bale, S., Bick, D., Das, S., Gastier-Foster, J., Grody, W. W., Hegde, M., Lyon, E., Spector, E., et al. (2015) Standards and guidelines for the interpretation of sequence variants: a joint consensus recommendation of the American College of Medical Genetics and Genomics and the Association for Molecular Pathology. Genet. Med. 17, 405–424.
Segurado Rodríguez, M. A., Ortiz De Frutos, F. J, Cornejo Navarro, P., Rodríguez Peralto, J. L., Sánchez Del Pozo, J., Guerra Tapia, A., and Iglesias Díez, L. (2002) Hypohidrotic ectodermal dysplasia: a cause of fever of unknown origin. An. Esp. Pediatr. 56, 253–257 (in Spanish).
Spfaer, J. A. (1981) A dental approach to carrier screening in X linked hypohidrotic ectodermal dysplasia. J. Med. Genet. 18, 459–460.
Wohlfart, S., Hammersen, J., and Schneider, H. (2016b) Mutational spectrum in 101 patients with hypohidrotic ectodermal dysplasia and breakpoint mapping in independent cases of rare genomic rearrangements. J. Hum. Genet, 61, 891–897.
Landrum, M. J., Lee, J. M., Benson, M., Brown, G. R., Chao, C., Chitipiralla, S., Gu, B., Hart, J., Hoffman, D., Jang, W., et al. (2018) ClinVar: improving ac
44
45
46
47
48
49
51
52
53
10
54
11
55
12
56
13
57
14
58
15
59
16
17
18
19
1
2
3
4
5
6
7
8
9
60
61
62
63
20
21
22
23
24
25
26
27
28
29
30
31
32
(50) 1975; 150
33
34
35
36
37
38
39
40
41
42
43
References_xml – reference: Yan, M., Zhang, Z., Brady, J. R., Schilbach, S., Fairbrother, W. J., and Dixit, V. M. (2002) Identification of a novel death domain-containing adaptor molecule for ectodysplasin-A receptor that is mutated in crinkled mice. Curr. Biol. 12, 409–413.
– reference: Suda, N., Bazar, A., Bold, O., Jigjid, B., Garidkhuu, A., Ganburged, G., and Moriyama, K. (2010) A Mongolian patient with hypohidrotic ectodermal dysplasia with a novel P121S variant in EDARADD. Orthod. Craniofac. Res. 13, 114–117.
– reference: Bibi, N., Ahmad, S., Ahmad, W., and Naeem, M. (2011) Molecular genetic analysis of consanguineous Pakistani families with autosomal recessive hypohidrotic ectodermal dysplasia. Australas J. Dermatol. 52, 37–42.
– reference: Yang, Y., Luo, L., Xu, J., Zhu, P., Xue, W., Wang, J., Li, W., Wang, M., Cheng, K., Liu, S., et al. (2013) Novel EDA p.Ile260Ser mutation linked to non-syndromic hypodontia. J. Dent. Res. 92, 500–506.
– reference: Kawai, T., Nishikomori, R., Izawa, K., Murata, Y., Tanaka, N., Sakai, H., Saito, M., Yasumi, T., Takaoka, Y., Nakahata, T., et al. (2012) Frequent somatic mosaicism of NEMO in T cells of patients with X-linked anhidrotic ectodermal dysplasia with immunodeficiency. Blood 119, 5458–5466.
– reference: Keng, S. B. (1984) Oro-facial manifestation of hypohidrotic ectodermal dysplasia—case report. Ann. Acad. Med. Singap. 13, 552–555.
– reference: Liu, N., Shi, H.-r., Wu, Q.-h., Jiang, M., and Kong, X.-d. (2013) Mutation analysis and first-trimester prenatal diagnosis for a Chinese family with hidrotic ectodermal dysplasia. Chinese journal of medical genetics 30, 407–409.
– reference: Hayashi, R., Farooq, M., Fujikawa, H., Fujimoto, A., Hashimoto, T., Ito, M., and Shimomura, Y. (2013) Case of hypohidrotic ectodermal dysplasia caused by a large deletion mutation in the EDA gene. J. Dermatol. 40, 281–283.
– reference: Liu, Y., Yu, X., Wang, L., Li, C., Archacki, S., Huang, C., Liu, J. Y., Wang, Q., Liu, M., and Tang, Z. (2012) Mutation p.Leu354Pro in EDA causes severe hypohidrotic ectodermal dysplasia in a Chinese family. Gene 491, 246–250.
– reference: Nikopensius, T., Annilo, T., Jagomägi, T., Gilissen, C., Kals, M., Krjutškov, K., Mägi, R., Eelmets, M., Gerst-Talas, U., Remm, M., et al. (2013) Non-syndromic tooth agenesis associated with a nonsense mutation in ectodysplasin-A (EDA). J. Dent. Res. 92, 507–511.
– reference: Rentzsch, P., Witten, D., Cooper, G. M., Shendure, J., and Kircher, M. (2019) CADD: predicting the deleteriousness of variants throughout the human genome. Nucleic Acids Res. 47, D886–D894.
– reference: Richards, S., Aziz, N., Bale, S., Bick, D., Das, S., Gastier-Foster, J., Grody, W. W., Hegde, M., Lyon, E., Spector, E., et al. (2015) Standards and guidelines for the interpretation of sequence variants: a joint consensus recommendation of the American College of Medical Genetics and Genomics and the Association for Molecular Pathology. Genet. Med. 17, 405–424.
– reference: Mikkola, M. L. (2009) Molecular aspects of hypohidrotic ectodermal dysplasia. Am. J. Med. Genet. A 149A, 2031–2036.
– reference: Nishikomori, R., Akutagawa,H., Maruyama, K., Nakata-Hizume, M., Ohmori, K., Mizuno, K., Yachie, A., Yasumi, T., Kusunoki, T., Heike, T., et al. (2004) X-linked ectodermal dysplasia and immunodeficiency caused by reversion mosaicism of NEMO reveals a critical role for NEMO in human T-cell development and/or survival. Blood 103, 4565–4572.
– reference: Lexner, M. O., Bardow, A., Hertz, J. M., Nielsen, L. A., and Kreiborg, S. (2007) Anomalies of tooth formation in hypohidrotic ectodermal dysplasia. Int. J. Paediatr. Dent. 17, 10–18.
– reference: Karczewski, K. J., Francioli, L. C., Tiao, G., Cummings, B. B., Alföldi, J., Wang, Q., Collins, R. L., Laricchia, K. M., Ganna, A., Birnbaum, D. P., et al. (2020) The mutational constraint spectrum quantified from variation in 141,456 humans. Nature 581, 434–443.
– reference: Tape, M. W., and Tye, E. (1995) Ectodermal dysplasia: literature review and a case report. Compend. Contin. Educ. Dent. 16, 524–528.
– reference: Chassaing, N., Cluzeau, C., Bal, E., Guigue, P., Vincent, M.-C., Viot, G., Ginisty, D., Munnich, A., Smahi, A., and Calvas, P. (2010) Mutations in EDARADD account for a small proportion of hypohidrotic ectodermal dysplasia cases. Br. J. Dermatol. 162, 1044–1048.
– reference: Cluzeau, C., Hadj-Rabia, S., Jambou, M., Mansour, S., Guigue, P., Masmoudi, S., Bal, E., Chassaing, N., Vincent, M.-C., Viot, G., et al. (2011) Only four genes (EDA1, EDAR, EDARADD, and WNT10A) account for 90% of hypohidrotic/anhidrotic ectodermal dysplasia cases. Hum. Mutat. 32, 70–72.
– reference: Viljoen, D. L., and Winship, W. S. (1988) A new form of hypohidrotic ectodermal dysplasia. Am. J. Med. Genet. 31, 25–32.
– reference: Barbaro, V., Confalonieri, L., Vallini, I., Ferrari, S., Ponzin, D., Mantero, G., Willoughby, C. E., Parekh, M., and Di Iorio, E. (2012) Development of an allele-specific real-time PCR assay for discrimination and quantification of p63 R279H mutation in EEC syndrome. J. Mol. Diagn. 14, 38–45.
– reference: Ersoy-Evans, S., Erkin, G., Fassihi, H., Chan, I., Paller, A. S., Sürücü, S., and McGrath, J. A. (2006) Ectodermal dysplasia-skin fragility syndrome resulting from a new homozygous mutation, 888delC, in the desmosomal protein plakophilin 1. J. Am. Acad. Dermatol. 55, 157–161.
– reference: Rifai, L., Port-Lis, M., Tabet, A. C., Bailleul-Forestier, I., Benzacken, B., Drunat, S., Kuzbari, S., Passemard, S., Verloes, A., and Aboura, A. (2010) Ectodermal dysplasia-like syndrome with mental retardation due to contiguous gene deletion: further clinical and molecular delineation of del(2q32) syndrome. Am. J. Med. Genet. A 152A, 111–117.
– reference: Farooq, M., Kurban, M., Fujimoto, A., Fujikawa, H., Abbas, O., Nemer, G., Saliba, J., Sleiman, R., Tofaili, M., Kibbi, A.-G., et al. (2013) A homozygous frameshift mutation in the HOXC13 gene underlies pure hair and nail ectodermal dysplasia in a Syrian family. Hum. Mutat. 34, 578–581.
– reference: Landrum, M. J., Lee, J. M., Benson, M., Brown, G. R., Chao, C., Chitipiralla, S., Gu, B., Hart, J., Hoffman, D., Jang, W., et al. (2018) ClinVar: improving access to variant interpretations and supporting evidence. Nucleic Acids Res. 46, D1062–D1067.
– reference: Wohlfart, S., Söder, S, Smahi, A., and Schneider, H. (2016a) A novel missense mutation in the gene EDARADD associated with an unusual phenotype of hypohidrotic ectodermal dysplasia. Am. J. Med. Genet. A 170A, 249–253.
– reference: Nijs, E. L., and Huisman, T. A. (2001) Recurrent fever and lack of tooth buds. A case of ectodermal dysplasia in a 9 months old boy. JBR-BTR 84, 256–257.
– reference: Morlon, A., Munnich, A., and Smahi, A. (2005) TAB2, TRAF6 and TAK1 are involved in NF-κB activation induced by the TNF-receptor, Edar and its adaptator Edaradd. Hum. Mol. Genet. 14, 3751–3757.
– reference: Aydin, M., Rencuzogullari, E., Bayram, S., Sevgiler, Y., and Genc, A. (2017) Alterations on high HbF levels may be associated with KLF1 gene mutations. Cell. Mol. Biol. 63, 51–57.
– reference: Freire-Maia, N., Fortes, V. A., Pereira, L. C., Opitz, J. M., Marcalle, F. A., and Cavalli, I. J. (1975) A syndrome of hypohidrotic ectodermal dysplasia with normal teeth, peculiar facies, pigmentary disturbances, psychomotor and growth retardation, bilateral nuclear cataract, and other signs. J. Med. Genet. 12, 308–310.
– reference: Norval, E. J., van Wyk, C. W., Basson, N. J., and Coldrey, J. (1988) Hypohidrotic ectodermal dysplasia: a genealogic, stereomicroscope, and scanning electron microscope study. Pediatr. Dermatol. 5, 159–166.
– reference: Vierucci, S., Baccetti, T., and Tollaro, I. (1994) Dental and craniofacial findings in hypohidrotic ectodermal dysplasia during the primary dentition phase. J. Clin. Pediatr. Dent. 18, 291–297.
– reference: Chen, L., Zhao, Y.-y., Wei, Y., Wang, Y., Zhang, Y., Wang, Y.-q., Liu, J.-y., Yang, Y., and Tan, Y.-h. (2012) Prenatal diagnosis of anhidrotic ectodermal dysplasia with unconventional loci abnormalities, a case report. Chin. Med. J. 125, 3177–3179.
– reference: Sun, X., Shen, J., Wu, W., Xie, J., Gao, C., Qin, L., Cui, Y., and Liu, J. (2013) Identification of a novel c.822 G>T mutation of EDA gene in a Chinese family with X-linked hypohidrotic ectodermal dysplasia. Chinese journal of medical genetics 30, 270–273 (in Chinese).
– reference: Baskan Ülkü, S. Z., and Yavuz, I. (2011) Ektodermal displazili hastalarda ptotetik yaklasimlar (Prosthetic approaches in ectodermal dysplasia patients). J. Dent. Fac. Atatürk Uni. 21, 57–61 (in Turkish).
– reference: Li, W., Gao, B.-d., Li, L.-y., Xiao, H. M., and Lu, G.-x. (2006) Mutation screening and prenatal diagnosis of hidrotic ectodermal dysplasia in a Chinese family. Chinese journal of medical genetics 23, 618–621 (in Chinese).
– reference: Yoshioka, T., Nishikomori, R., Hara, J., Okada, K., Hashii, Y., Okafuji, I., Nodomi, S., Kawai, T., Izawa, K., Ohnishi, H., et al. (2013) Autosomal dominant anhidrotic ectodermal dysplasia with immunodeficiency caused by a novel NFKBIA mutation, p.Ser36Tyr, presents with mild ectodermal dysplasia and non-infectious systemic inflammation. J. Clin. Immunol. 33, 1165–1174.
– reference: Ahmed, H. A., El-Kamah, G. Y., Rabie, E., Mostafa, M. I., Abouzaid, M. R., Hassib, N. F., Mehrez, M. I., Abdel-Kader, M. A., Mohsen, Y. H., Zada, S. K., et al. (2021) Gene mutations of the three ectodysplasin pathway key players (EDA, EDAR, and EDARADD) account for more than 60% of Egyptian ectodermal dysplasia: a report of seven novel mutations. Genes (Basel) 12, 1389.
– reference: Martínez-Romero, M. C., Ballesta-Martínez, M. J., López-González, V., Sánchez-Soler, M. J., Serrano-Antón, A. T., Barreda-Sánchez, M., Rodriguez-Peña, L., Martínez-Menchon, M. T., Frías-Iniesta, J., Sánchez-Pedreño, P., et al. (2019) EDA, EDAR, EDARADD and WNT10A allelic variants in patients with ectodermal derivative impairment in the Spanish population. Orphanet J. Rare Dis. 14, 281–291.
– reference: Wohlfart, S., Hammersen, J., and Schneider, H. (2016b) Mutational spectrum in 101 patients with hypohidrotic ectodermal dysplasia and breakpoint mapping in independent cases of rare genomic rearrangements. J. Hum. Genet, 61, 891–897.
– reference: Yin, W., Ye, X., and Bian, Z. (2013) The second deletion mutation in exon 8 of EDA gene in an XLHED pedigree. Dermatology 226, 105–110.
– reference: Monreal, A. W., Zonana, J., and Ferguson, B. (1998) Identification of a new splice form of the EDA1 gene permits detection of nearly all X-linked hypohidrotic ectodermal dysplasia mutations. Am. J. Hum. Genet. 63, 380–399.
– reference: Baskan, Z., Yavuz, I., Ulku, R., Kaya, S., Yavuz, Y., Basaran, G., Adiguzel, O., and Ozer, T. (2006) Evaluation of ectodermal dysplasia. Kaohsiung J. Med. Sci. 22, 171–176.
– reference: Schindler, A., Guazzarotti, L., Mameli, C., Urbani, E., Mozzanica, F., Guerrini, L., and Zuccotti, G. V. (2013) Vomer aplasia in a patient carrying a de novo mutation of the TP63 gene (3q27). Int. J. Pediatr. Otorhinolaryngol. 77, 1606–1608.
– reference: Rodewald, A., and Zahn-Messow, K. (1982) Dermatoglyphics findings in families with X-linked hypohidrotic (or anhidrotic) ectodermal dysplasia (HED). Prog. Clin. Biol. Res. 84, 451–458.
– reference: Shoenfeld, Y., Shapiro, Y., Fisher, B. K., and Dvoretzky, I. (1975) Sweating in the ‘anhidrotic type’ of congenital ectodermal dysplasia. Dermatologica 150, 277–282.
– reference: Lefebvre, S., and Mikkola, M. L. (2014) Ectodysplasin research—where to next? Semin. Immunol. 26, 220–228.
– reference: Bal, E., Baala, L., Cluzeau, C., El Kerch, F., Ouldim, K., Hadj-Rabia, S., Bodemer, C., Munnich, A., Courtois, G., Sefiani, A., et al. (2007) Autosomal dominant anhidrotic ectodermal dysplasias at the EDARADD locus. Hum. Mutat. 28, 703–709.
– reference: Salvi, A., Giacopuzzi, E., Bardellini, E., Amadori, F., Ferrari, L., De Petro, G., Borsani, G., and Majorana, A. (2016) Mutation analysis by direct and whole exome sequencing in familial and sporadic tooth agenesis. Int. J. Mol. Med. 38, 1338–1348.
– reference: Koguchi-Yoshioka, H., Wataya-Kaneda, M., Yutani, M., Nakano, H., Sawamura, D., and Katayama, I. (2015) Partial anhidrosis demonstrated by Q-SART in a patient with a novel mutation in the EDARADD gene. J. Eur. Acad. Dermatol. Venereol. 29, 1443–1444.
– reference: Monreal, A. W., Ferguson, B. M., Headon, D. J., Street, S. L., Overbeek, P. A., and Zonana, J. (1999) Mutations in the human homologue of mouse dl cause autosomal recessive and dominant hypohidrotic ectodermal dysplasia. Nat. Genet. 22, 366–369.
– reference: Segurado Rodríguez, M. A., Ortiz De Frutos, F. J, Cornejo Navarro, P., Rodríguez Peralto, J. L., Sánchez Del Pozo, J., Guerra Tapia, A., and Iglesias Díez, L. (2002) Hypohidrotic ectodermal dysplasia: a cause of fever of unknown origin. An. Esp. Pediatr. 56, 253–257 (in Spanish).
– reference: Chaudhary, A. K., Girisha, K. M., and Bashyam, M. D. (2016) A novel EDARADD 5’-splice site mutation resulting in activation of two alternate cryptic 5’-splice sites causes autosomal recessive Hypohidrotic Ectodermal Dysplasia. Am. J. Med. Genet. A 170, 1639–1641.
– reference: Asamoah, A., Decker, A. B., Wiktor, A., and Van Dyke, D. L. (2003) Child with De Novo t(1;6)(p22.1;p22.1) translocation and features of ectodermal dysplasia with hypodontia and developmental delay. Am. J. Med. Genet. A 118A, 82–85.
– reference: Shi, H.-j., Fang, Q., and Wang, L.-t. (2005) Prenatal diagnosis of X-linked anhidrotic ectodermal dysplasia with X-chromosome inversion. Chin Med. J. 85, 1845–1848 (in Chinese).
– reference: Callea, M., Teggi, R., Yavuz, I., Tadini, G., Priolo, M., Crovella, S., Clarich, G., and Grasso, D. L. (2013) Ear nose throat manifestations in hypoidrotic ectodermal dysplasia. Int. J. Pediatr. Otorhinolaryngol. 77, 1801–1804.
– reference: Headon, D. J., Emmal, S. A., Ferguson, B. M., Tucker, A. S., Justice, M. J., Sharpe, P. T., Zonana, J., and Overbeek, P. A. (2001) Gene defect in ectodermal dysplasia implicates a death domain adapter in development. Nature 414, 913–916.
– reference: Mousumi, T., Xiong, Z., Lu, L., Liu, S., Xia, K., and Hu, Z. (2013) Identification of a known GJB6 mutation in an autosomal dominant inherited Chinese family with hidrotic ectodermal dysplasia. Journal of Central South University, Medical sciences 38, 761–765.
– reference: Potter, P. C., and Bowie, M. D. (1984) Dysphagia in hypohidrotic ectodermal dysplasia. A case report. S. Afr. Med. J. 66, 232–234.
– reference: Wang, H. J., Tang, Z. L., Lin, Z. M., Dai, L. L., Chen, Q., and Yang, Y. (2014) Recurrent splice-site mutation in MBTPS2 underlying IFAP syndrome with Olmsted syndrome-like features in a Chinese patient. Clin. Exp. Dermatol. 39, 158–161.
– reference: Haghighi, A., Nikuei, P., Haghighi-Kakhki, H., Saleh-Gohari, N., Baghestani, S., Krawitz, P. M., Hecht, J., and Mundlos, S. (2013) Whole-exome sequencing identifies a novel missense mutation in EDAR causing autosomal recessive hypohidrotic ectodermal dysplasia with bilateral amastia and palmoplantar hyperkeratosis. Br. J. Dermatol. 168, 1353–1356.
– reference: Feng, H.-l., Zhang, X.-x., and Wu, H. (2007) Research advances in tooth agenesis. Journal of Peking University, Health sciences 39, 13–17 (in Chinese).
– reference: Spfaer, J. A. (1981) A dental approach to carrier screening in X linked hypohidrotic ectodermal dysplasia. J. Med. Genet. 18, 459–460.
– ident: 27
  doi: 10.1111/j.1365-263X.2006.00801.x
– ident: 20
  doi: 10.1038/414913a
– ident: 56
  doi: 10.1002/ajmg.1320310106
– ident: 2
  doi: 10.1002/ajmg.a.10929
– ident: 42
  doi: 10.1093/nar/gky1016
– ident: 12
– ident: 5
  doi: 10.1016/j.jmoldx.2011.07.008
– ident: 40
  doi: 10.1111/j.1525-1470.1988.tb01162.x
– ident: 43
  doi: 10.1038/gim.2015.30
– ident: 34
  doi: 10.1086/301984
– ident: 16
– ident: 55
– ident: 7
  doi: 10.1016/S1607-551X(09)70303-1
– ident: 11
  doi: 10.1002/ajmg.a.37607
– ident: 49
– ident: 51
  doi: 10.1136/jmg.18.6.459
– ident: 1
  doi: 10.3390/genes12091389
– ident: 45
– ident: 41
– ident: 38
  doi: 10.1177/0022034513487210
– ident: 54
– ident: 58
  doi: 10.1002/ajmg.a.37412
– ident: 4
  doi: 10.1002/humu.20500
– ident: 28
  doi: 10.1016/S1472-6483(11)60543-9
– ident: 21
  doi: 10.1038/s41586-020-2308-7
– ident: 33
  doi: 10.1038/11937
– ident: 47
  doi: 10.1016/j.ijporl.2013.06.027
– ident: 23
– ident: 25
  doi: 10.1093/nar/gkx1153
– ident: 59
  doi: 10.1038/jhg.2016.75
– ident: 62
  doi: 10.1159/000346610
– ident: 57
  doi: 10.1111/ced.12248
– ident: 61
  doi: 10.1177/0022034513487557
– ident: 37
– ident: 32
  doi: 10.1002/ajmg.a.32855
– ident: 17
  doi: 10.1136/jmg.12.3.308
– ident: 46
  doi: 10.3892/ijmm.2016.2742
– ident: 60
  doi: 10.1016/S0960-9822(02)00687-5
– ident: 13
  doi: 10.1002/humu.21384
– volume: 150
  start-page: 277
  issn: 0011-9075
  year: 1975
  ident: 50
  publication-title: Dermatologica
  doi: 10.1159/000251442
– ident: 53
– ident: 10
  doi: 10.1111/j.1365-2133.2010.09670.x
– ident: 3
  doi: 10.14715/cmb/2017.63.8.12
– ident: 63
  doi: 10.1007/s10875-013-9924-z
– ident: 22
  doi: 10.1182/blood-2011-05-354167
– ident: 35
  doi: 10.1093/hmg/ddi405
– ident: 52
  doi: 10.1111/j.1601-6343.2010.01484.x
– ident: 30
  doi: 10.1016/j.gene.2011.10.009
– ident: 36
– ident: 8
  doi: 10.1111/j.1440-0960.2010.00685.x
– ident: 15
  doi: 10.1002/humu.22271
– ident: 29
– ident: 14
  doi: 10.1016/j.jaad.2005.10.002
– ident: 48
  doi: 10.1016/S1695-4033(02)77793-X
– ident: 19
  doi: 10.1111/1346-8138.12077
– ident: 26
  doi: 10.1016/j.smim.2014.05.002
– ident: 9
  doi: 10.1016/j.ijporl.2013.09.004
– ident: 24
  doi: 10.1111/jdv.12493
– ident: 6
– ident: 31
  doi: 10.1186/s13023-019-1251-x
– ident: 39
  doi: 10.1182/blood-2003-10-3655
– ident: 18
  doi: 10.1111/bjd.12151
– ident: 44
  doi: 10.1002/ajmg.a.33164
SSID ssj0020983
Score 2.326378
Snippet Ectodermal dysplasia (ED), which exhibits a wide range of clinical symptoms, may be classified into three major types: hypohidrotic, anhidrotic, and hidrotic....
SourceID proquest
pubmed
crossref
jstage
SourceType Aggregation Database
Index Database
Publisher
StartPage 171
SubjectTerms anhidrotic
Anhidrotic ectodermal dysplasia
Biopsy
Child
Death Domain
ectodermal dysplasia
Ectodermal Dysplasia - genetics
Ectodermal Dysplasia 1, Anhidrotic - genetics
Ectodermal Dysplasia 1, Anhidrotic - pathology
Ectodysplasin
Edar-Associated Death Domain Protein - genetics
EDARADD
Endonuclease
Female
Genetic analysis
Genetic disorders
Humans
Male
Medical diagnosis
MnII restriction endonuclease
Mutation
new mutation
Pedigree
Polymorphism
Polymorphism, Restriction Fragment Length
Receptors, Ectodysplasin - genetics
Restriction fragment length polymorphism
Sweat gland
Teeth
Title A new variant of the ectodysplasin A receptor death domain gene associated with anhidrotic ectodermal dysplasia in a Turkish family and its simple diagnosis by restriction fragment length polymorphism
URI https://www.jstage.jst.go.jp/article/ggs/98/4/98_22-00138/_article/-char/en
https://www.ncbi.nlm.nih.gov/pubmed/37673591
https://www.proquest.com/docview/2901977273
https://www.proquest.com/docview/2862199713
Volume 98
WOSCitedRecordID wos001072006300001&url=https%3A%2F%2Fcvtisr.summon.serialssolutions.com%2F%23%21%2Fsearch%3Fho%3Df%26include.ft.matches%3Dt%26l%3Dnull%26q%3D
hasFullText 1
inHoldings 1
isFullTextHit
isPrint
ispartofPNX Genes & Genetic Systems, 2023/08/01, Vol.98(4), pp.171-178
journalDatabaseRights – providerCode: PRVAON
  databaseName: DOAJ Directory of Open Access Journals
  customDbUrl:
  eissn: 1880-5779
  dateEnd: 99991231
  omitProxy: false
  ssIdentifier: ssj0020983
  issn: 1341-7568
  databaseCode: DOA
  dateStart: 20120101
  isFulltext: true
  titleUrlDefault: https://www.doaj.org/
  providerName: Directory of Open Access Journals
link http://cvtisr.summon.serialssolutions.com/2.0.0/link/0/eLvHCXMwtZ1Lb9NAEIBXTWklLog3gVINEpwil9jxa8UpoCLEoeIQpNystb0OgdSO7CSq-wv5Wczsw3GFkKgQF8tar3c3mc-7M_uYYex1QEKNfN-RUnqOL8PQEZnMHLLEPDEOPF_kKthEdHERz-f8y8Hg2J6F2a2isoyvrvj6v4oa01DYdHT2FuLuCsUEvEeh4xXFjte_EvyUooSPdmgDC73Mr7ZtZJsqb5s1HZossTPAfk6u0dwe5aQCjvLqUmA6lilHwgjM7ksX5bdlXlfk2FWVQl35amQLEzRhIkazbf2DfCOZ-RK7ItEsyfkwTfDSfr5lQ8ouBQOplzpCeVGLhdqNQPFcsK51tWovKxS9dWxo1GZyjt0oSumOmtL3tE7rRSiB7XW1QINa6LPz521rJtXIXrjWZL4X5Ra_ip05_2ZmO7xJt9dO86m-HV1R0-1rxX_yM2oWZa8bx7HZiQIdsOdM6jTsqZwg0qFrbN_P4x7jfq8jd3VgGKMTuDrM0G_DDWo3iMNi0ZyhSa8WfffDarfZ0ZCQYLaEx4lPF89LVPbEPqQzdkjvgN3xooBzOzdgZg7GXPmT7X6WOcGB1b_tV35Dtzr6jubFQv7ZclIa1Ow-u2dMH5jqtjxgB7J8yI51MNT2Efs5BQQXDLhQFYDgwg1wYQoWXFDgggYXCFzYgwsELuzBhT240IEL-J4AAy5ocPGdHBBc0OBCBy6kLfTABQsuaHChD-5j9vXj-ezDJ8fEGXEyP5xsnLAI3bAY5xxtG9fNvEnm-4XrStScs0CSi7p04grpo3Ys0lCmQZajXRQKn6fcc1ELfMIOy6qUzxikBRf5uMjzCA2NKAu454dpiko5DzM3Hcshe2MllKy1O5mEzHCUpOLDcjFk77T4uly3oWjITqzME9MzYdGo-aOxh-bKkL3qHuNgQiuEopTVFvPEoUc7z1zM81Sz0jWA3D5NAu4-_6emvWB395_1CTvc1Fv5kh1lu82yqU_ZIJrHp4r9X2hpDBs
linkProvider Directory of Open Access Journals
openUrl ctx_ver=Z39.88-2004&ctx_enc=info%3Aofi%2Fenc%3AUTF-8&rfr_id=info%3Asid%2Fsummon.serialssolutions.com&rft_val_fmt=info%3Aofi%2Ffmt%3Akev%3Amtx%3Ajournal&rft.genre=article&rft.atitle=A+new+variant+of+the+ectodysplasin+A+receptor+death+domain+gene+associated+with+anhidrotic+ectodermal+dysplasia+in+a+Turkish+family+and+its+simple+diagnosis+by+restriction+fragment+length+polymorphism&rft.jtitle=Genes+%26+Genetic+Systems&rft.au=Rencuzogullari%2C+Eyyup&rft.au=Ezer%2C+Banu+Guven&rft.date=2023-08-01&rft.pub=The+Genetics+Society+of+Japan&rft.issn=1341-7568&rft.eissn=1880-5779&rft.volume=98&rft.issue=4&rft.spage=171&rft.epage=178&rft_id=info:doi/10.1266%2Fggs.22-00138&rft.externalDocID=article_ggs_98_4_98_22_00138_article_char_en
thumbnail_l http://covers-cdn.summon.serialssolutions.com/index.aspx?isbn=/lc.gif&issn=1341-7568&client=summon
thumbnail_m http://covers-cdn.summon.serialssolutions.com/index.aspx?isbn=/mc.gif&issn=1341-7568&client=summon
thumbnail_s http://covers-cdn.summon.serialssolutions.com/index.aspx?isbn=/sc.gif&issn=1341-7568&client=summon